Biomed J 2021 Apr 11;44(2):223-226. Epub 2021 Apr 11.
Division of Trauma Plastic Surgery, Department of Plastic and Reconstructive Surgery, Chang Gung Memorial Hospital at Linkou, Taoyuan, Taiwan; Craniofacial Research Center, Chang Gung Memorial Hospital at Taoyuan, Taoyuan, Taiwan; College of Medicine, Chang Gung University, Taoyuan, Taiwan; Xiamen Chang Gung Hospital, Xiamen, China. Electronic address:
Harlequin ichthyosis is a rare congenital disorder, which causes restrictive circumferential encasement of the trunk and limbs. Patients usually develop compartment syndrome and sequential cyanosis of limbs and digits, leading to autoamputation. We report a case of harlequin ichthyosis in which all digits were preserved with an early escharotomy-like procedure. Read More